5-oxoprolinase deficiency

MeSH: C535322ORPHA: 33572

Overview

5-Oxoprolinase deficiency is clinically a very heterogeneous condition characterized by 5-oxoprolinuria

Available Treatments (0)

No treatments linked yet

Clinical trials or compassionate use may be available — consult a specialist.

Clinical Presentation

Signs and symptoms associated with 5-oxoprolinase deficiency, sourced from HPO and Orphanet clinical annotations.

Feeding difficulties in infancyFloppy infantExcessive daytime somnolenceReduced circulating 5-oxoprolinase activityIncreased level of L-pyroglutamic acid in urineGlobal developmental delayMicrocephalyStrabismusDelayed speech and language developmentNephrolithiasisJaundiceSeizureHypotoniaFailure to thriveMetabolic acidosisHypoglycemiaCerebral atrophyEnterocolitisPostnatal macrocephaly

Classification & Codes

MeSH Code

C535322

Orphanet Code

ORPHA:33572
5-oxoprolinase deficiency
MeSHC535322
OrphanetORPHA:33572
Treatments0 drug(s)
Symptoms on record19 signs
Statuspublished
Factual Authority
Last Updated3/20/2026
Clinical DataHPO · Orphanet
Drug DataFDA · EMA · CDSCO
5-oxoprolinase deficiency | OrphanDrug